Treatment of human disease by adeno-associated viral gene transfer
- 13 April 2006
- journal article
- review article
- Published by Springer Nature in Human Genetics
- Vol. 119 (6), 571-603
- https://doi.org/10.1007/s00439-006-0165-6
Abstract
During the past decade, in vivo administration of viral gene transfer vectors for treatment of numerous human diseases has been brought from bench to bedside in the form of clinical trials, mostly aimed at establishing the safety of the protocol. In preclinical studies in animal models of human disease, adeno-associated viral (AAV) vectors have emerged as a favored gene transfer system for this approach. These vectors are derived from a replication-deficient, non-pathogenic parvovirus with a single-stranded DNA genome. Efficient gene transfer to numerous target cells and tissues has been described. AAV is particularly efficient in transduction of non-dividing cells, and the vector genome persists predominantly in episomal forms. Substantial correction, and in some instances complete cure, of genetic disease has been obtained in animal models of hemophilia, lysosomal storage disorders, retinal diseases, disorders of the central nervous system, and other diseases. Therapeutic expression often lasted for months to years. Treatments of genetic disorders, cancer, and other acquired diseases are summarized in this review. Vector development, results in animals, early clinical experience, as well as potential hurdles and challenges are discussed.Keywords
This publication has 172 references indexed in Scilit:
- Intrastriatal rAAV-mediated delivery of anti-huntingtin shRNAs induces partial reversal of disease progression in R6/1 Huntington's disease transgenic miceMolecular Therapy, 2005
- Semaphorin 4B interacts with the post‐synaptic density protein PSD‐95/SAP90 and is recruited to synapses through a C‐terminal PDZ‐binding motifFEBS Letters, 2005
- Restoration of aspartoacylase activity in CNS neurons does not ameliorate motor deficits and demyelination in a model of Canavan diseaseMolecular Therapy, 2005
- Leptin resistance exacerbates diet-induced obesity and is associated with diminished maximal leptin signalling capacity in ratsDiabetologia, 2005
- Sonic hedgehog delivered by an adeno-associated virus protects dopaminergic neurones against 6-OHDA toxicity in the ratJournal of Neural Transmission, 2004
- Restriction of neuroblastoma angiogenesis and growth by interferon-α/βSurgery, 2004
- Micro-dystrophin cDNA ameliorates dystrophic phenotypes when introduced into mdx mice as a transgeneBiochemical and Biophysical Research Communications, 2002
- Self-assembly of polyglutamine-containing huntingtin fragments into amyloid-like fibrils: Implications for Huntington’s disease pathologyProceedings of the National Academy of Sciences, 1999
- Cell Lines for the Production of Recombinant Adeno-Associated VirusHuman Gene Therapy, 1995
- Analysis of a dystrophin gene deletion by amplification of mRNA isolated from DMD myotubes cultured in vitroGenomics, 1991